Development of a new expanded next‐generation sequencing panel for genetic diseases involved in dyslipidemia - Archive ouverte HAL
Article Dans Une Revue Clinical Genetics Année : 2020

Development of a new expanded next‐generation sequencing panel for genetic diseases involved in dyslipidemia

Oriane Marmontel
Pierre Antoine Rollat-Farnier
  • Fonction : Auteur
Anne‐sophie Wozny
  • Fonction : Auteur
Sybil Charrière
  • Fonction : Auteur
Xavier Vanhoye
  • Fonction : Auteur
Thomas Simonet
  • Fonction : Auteur
Nicolas Chatron
Delphine Collin-Chavagnac
  • Fonction : Auteur
Séverine Nony
  • Fonction : Auteur
Sabrina Dumont
  • Fonction : Auteur
Muriel Mahl
  • Fonction : Auteur
Chantal Jacobs
  • Fonction : Auteur
Alexandre Janin
Cyrielle Caussy
  • Fonction : Auteur
Pierre Poinsot
  • Fonction : Auteur
Igor Tauveron
  • Fonction : Auteur
Gilles Millat
Noël Peretti
  • Fonction : Auteur
Philippe Moulin
  • Fonction : Auteur
Christophe Marçais
  • Fonction : Auteur
Mathilde Di Filippo
  • Fonction : Auteur

Résumé

Abstract The aim of this study was to provide an efficient tool: reliable, able to increase the molecular diagnosis performance, to facilitate the detection of copy number variants (CNV), to assess genetic risk scores (wGRS) and to offer the opportunity to explore candidate genes. Custom SeqCap EZ libraries, NextSeq500 sequencing and a homemade pipeline enable the analysis of 311 dyslipidemia‐related genes. In the training group (48 DNA from patients with a well‐established molecular diagnosis), this next‐generation sequencing (NGS) workflow showed an analytical sensitivity >99% (n = 532 variants) without any false negative including a partial deletion of one exon. In the prospective group, from 25 DNA from patients without prior molecular analyses, 18 rare variants were identified in the first intention panel genes, allowing the diagnosis of monogenic dyslipidemia in 11 patients. In six other patients, the analysis of minor genes and wGRS determination provided a hypothesis to explain the dyslipidemia. Remaining data from the whole NGS workflow identified four patients with potentially deleterious variants. This NGS process gives a major opportunity to accede to an enhanced understanding of the genetic of dyslipidemia by simultaneous assessment of multiple genetic determinants.
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Dates et versions

hal-04383017 , version 1 (09-01-2024)

Identifiants

Citer

Oriane Marmontel, Pierre Antoine Rollat-Farnier, Anne‐sophie Wozny, Sybil Charrière, Xavier Vanhoye, et al.. Development of a new expanded next‐generation sequencing panel for genetic diseases involved in dyslipidemia. Clinical Genetics, 2020, 98 (6), pp.589-594. ⟨10.1111/cge.13832⟩. ⟨hal-04383017⟩
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