Role of MDH2 pathogenic variant in pheochromocytoma and paraganglioma patients - Archive ouverte HAL
Article Dans Une Revue Genetics in Medicine Année : 2018

Role of MDH2 pathogenic variant in pheochromocytoma and paraganglioma patients

Bruna Calsina
  • Fonction : Auteur
Maria Currás-Freixes
  • Fonction : Auteur
Tirso Pons
  • Fonction : Auteur
Laura Contreras
  • Fonction : Auteur
Rocío Letón
  • Fonction : Auteur
Iñaki Comino-Méndez
  • Fonction : Auteur
Laura Remacha
  • Fonction : Auteur
María Calatayud
  • Fonction : Auteur
Berta Obispo
  • Fonction : Auteur
Regis Cohen
  • Fonction : Auteur
Susan Richter
  • Fonction : Auteur
Judith Balmaña
  • Fonction : Auteur
Esther Korpershoek
  • Fonction : Auteur
Elena Rapizzi
  • Fonction : Auteur
Timo Deutschbein
  • Fonction : Auteur
Laurent Vroonen
  • Fonction : Auteur
Ronald de Krijger
  • Fonction : Auteur
Martin Fassnacht
  • Fonction : Auteur
Felix Beuschlein
  • Fonction : Auteur
Henri Timmers
  • Fonction : Auteur
Graeme Eisenhofer
  • Fonction : Auteur
Massimo Mannelli
  • Fonction : Auteur
Karel Pacak
  • Fonction : Auteur
Jorgina Satrústegui
  • Fonction : Auteur
Cristina Rodríguez-Antona
  • Fonction : Auteur
Alberto Cascón
  • Fonction : Auteur
Nicole Dölker
  • Fonction : Auteur
Mercedes Robledo
  • Fonction : Auteur

Résumé

Purpose To prospectively assess the clinical impact of expert review of lymphoma diagnosis in France. Materials and Methods From January 2010 to December 2013, 42,145 samples from patients with newly diagnosed or suspected lymphomas were reviewed, according to the 2008 WHO classification, in real time by experts through the Lymphopath Network. Changes in diagnosis between referral and expert review were classified as major or minor according to their potential impact on patient care. Results The 42,145 reviewed samples comprised 36,920 newly diagnosed mature lymphomas, 321 precursor lymphoid neoplasms, 314 myeloid disorders, and 200 nonhematopoietic neoplasms, with 4,390 benign lesions. There were 4,352 cutaneous and 32,568 noncutaneous lymphomas. The most common mature noncutaneous lymphomas were diffuse large B-cell lymphomas (32.4%), follicular lymphomas (15.3%), classic Hodgkin lymphomas (13%), peripheral T-cell lymphomas (6.3%) of which angioimmunoblastic T-cell lymphomas (2.3%) were the most frequent, and mucosa-associated lymphoid tissue lymphomas (5.8%). A diagnostic change between referral and expert review occurred in 19.7% of patients, with an estimated impact on patient care for 17.4% of patients. This rate was significantly higher for patients sent with a provisional diagnosis seeking expert second opinion (37.8%) than for patients sent with a formal diagnosis (3.7%). The most frequent discrepancies were misclassifications in lymphoma subtype (41.3%), with 12.3% being misclassifications among small B-cell lymphoma entities. Fewer than 2% of changes were between benign and malignant lymphoid conditions. Minor changes (2.3%) mostly consisted of follicular lymphoma misgrading and diffuse large B-cell lymphoma subtype misclassification. Conclusion To our knowledge, this study provides the largest ever description of the distribution of lymphoma entities in a western country and highlights how expert review significantly contributes to a precise lymphoma diagnosis and optimal clinical management in a proportion of patients.

Dates et versions

hal-03968208 , version 1 (01-02-2023)

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Citer

Bruna Calsina, Maria Currás-Freixes, Alexandre Buffet, Tirso Pons, Laura Contreras, et al.. Role of MDH2 pathogenic variant in pheochromocytoma and paraganglioma patients. Genetics in Medicine, 2018, 20 (12), pp.1652-1662. ⟨10.1038/s41436-018-0068-7⟩. ⟨hal-03968208⟩
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